Validation of epistaxis severity score for hereditary hemorrhagic telangiectasia in Japan.

Publication/Presentation Date

6-1-2022

Abstract

OBJECTIVE: This study aimed to assess the health-related QoL (HR-QoL) of patients with hereditary hemorrhagic telangiectasia (HHT), with emphasis on the role/social aspects, and validate the Japanese version of the epistaxis severity score (ESS) in these patients.

METHODS: The Japanese version of the ESS was created through forward and reverse translation, and consultation with the original author. A validation analysis was performed by comparing ESS severity with the invasiveness of previous treatments for epistaxis and assessing the correlation between the ESS and HR-QoL. Medical history forms, ESS questionnaires, and the Medical Outcomes Study Short Form 36 (SF-36) were distributed to participants with HHT in August 2020. The relation between the ESS and summary scores of SF-36 was assessed by performing analysis of variance and Spearman's correlation.

RESULTS: In total, 73 participants were included in this study. The average ESS was 5.02; there were mild (32.9%), moderate (45.2%), and severe (21.9%) epistaxis groups. Patients with higher ESS received a significantly more invasive treatment (Fisher's exact test, p <  0.05). The ESS was also negatively correlated with the physical component score (PCS) (r = -0.489, p <  0.001). Comorbid liver and gastrointestinal arteriovenous malformations significantly reduced the PCS (p <  0.05). Multiple regression analysis revealed that the ESS was a significant variable (p <  0.01). The role/social component score was significantly lower in the severe ESS group than in the mild or moderate group.

CONCLUSION: The Japanese version of the ESS was considered valid and may be useful as an outcome measure of future HHT-associated epistaxis trials in Japan.

Volume

49

Issue

3

First Page

415

Last Page

420

ISSN

1879-1476

Disciplines

Medicine and Health Sciences

PubMedID

34857410

Department(s)

Department of Medicine

Document Type

Article

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